Eosinophilic fasciitis in a 5-year-old boy
More details
Hide details
Submission date: 2013-03-07
Acceptance date: 2013-03-28
Online publication date: 2013-06-26
Publication date: 2013-06-28
Reumatologia 2013;51(3):225-228
Eosinophilic fasciitis is a rare disease in childhood. We report the case of a 5-year-old boy who was admitted to our hospital with a 2-month history of generalised skin sclerosis, induration, erythema, peau d’orange,
groove sign, and painless joint contractures of multiple joints, which was preceded by a week of high fever. Laboratory tests revealed a peripheral eosinophilia. A full-thickness biopsy of skin-muscle and fascia confirmed the diagnosis of eosinophilic fasciitis. The patient received prednisolone, methotrexate, chloroquine, and
rehabilitation. Five months later the following were observed: better general health, reduction of skin and subcutaneous hardening,and better mobility of joints. In conclusion, eosinophilic fasciitis ought to be taken into differential diagnosis of generalised scleroderma with joint contractures in children. Combination therapy allows for improvement of efficiency.
Kowal K, Kowal-Bielecka O. Eozynofilowe zapalenie powięzi. W: Reumatologia. Wielka interna. Puszczewicz M (red.). Medical Tribune Polska, Warszawa 2010; 142-147.
Grisanti MW, Moore TL, Osborn TG, Haber PL. Eosinophilic fasciitis in children. Semin Arthritis Rheum 1989; 19: 151-157.
Ortega-Loayza AG, Merritt BG, Groben PA, Morrell DS. Eosinophilic fasciitis in a female child. J Am Acad Dermatol 2008; 58 (5 Suppl 1): S72-S74.
Bobrowska-Snarska D, Ostanek L, Brzozko M. Eozynofilowe zapalenie powięzi. Opis 5 przypadków i przegląd literatury. Pol Arch Med Wew 2007; 117: 184-191.
Wisłowska M, Rok M, Matuszyk M. Eozynofilowe zapalenie powięzi – opis przypadku. Reumatologia 2005; 43: 35-38.
Wolański Ł, Otrocki P, Kachaniuk H. Rozlane zapalenie powięzi z eozynofilią i hipoalbuminemią. Reumatologia 2012; 50: 255-259.
Bobrowska-Snarska D, Ostanek L, Brzosko M. Eozynofilowe zapalenie powięzi – trudności diagnostyczne i terapeutyczne. Roczniki Pomorskiej Akademii Medycznej w Szczecinie 2008, 54: 47-51.
Horacek E, Sator PG, Gschnait F. 'Venous furrowing': a clue to the diagnosis of eosinophilic fasciitis. A case of eosinophilic fasciitis ultimately treated with oral PUVA therapy. Dermatology 2007; 215: 89-90.
Abeles M, Belin DC, Zurier RB. Eosinophilic fasciitis: a clinicopathologic study. Arch Intern Med 1979; 139: 586-588.
Chan V, Soans B, Mathers D. Ultrasound and magnetic resonance imaging features in a patient with eosinophilic fasciitis. Australas Radiol 2004; 48: 414-417.
Pillen S, van Engelen B, van den Hoogen F, et al. Eosinophilic fasciitis in a child mimicking a myopathy. Neuromuscul Disord 2006; 16: 144-148.
Quintero-Del-Rio AI, Punaro M, Pascual V. Faces of eosinophilic fasciitis in childhood. J Clin Rheumatol 2002; 8: 99-103.
Valencia IC, Chang A, Kirsner RS, Kerdel FA. Eosinophilic fasciitis responsive to treatment with pulsed steroids and cyclosporine. Int J Dermatol 1999; 38: 369-372.
Loupasakis K, Derk CT. Eosinophilic fasciitis in a pediatric patient. J Clin Rheumatol 2010; 16: 129-131.
Poliak N, Orange JS, Pawel BR, Weiss PF. Eosinophilic fasciitis mimicking angioedema and treatment response to infliximab in a pediatric patient. Ann Allergy Asthma Immunol 2011; 106: 444-5.
Pimenta S, Bernardes M, Bernardo A, et al. Intravenous immune globulins to treat eosinophilic fasciitis: a case report. Joint Bone Spine 2009; 76: 572-574.
Copyright: © Narodowy Instytut Geriatrii, Reumatologii i Rehabilitacji w Warszawie. This is an Open Access journal, all articles are distributed under the terms of the Creative Commons Attribution-NonCommercial-ShareAlike 4.0 International (CC BY-NC-SA 4.0) License (https://creativecommons.org/licenses/by-nc-sa/4.0/), allowing third parties to copy and redistribute the material in any medium or format and to remix, transform, and build upon the material, provided the original work is properly cited and states its license.
Journals System - logo
Scroll to top